Neuroendocrine Tumors                                                                                                                             193

36.  Neuroendocrine Tumors

36.1.      General considerations

Neuroendocrine tumors are uncommon and optimum management of patients should be by a multidisciplinary approach in centers of expertise!

Literature: for review

BRENTJENS and SALTZ, Surg. Clin. North Am. 81 (2001): 527-542 (islet cell tumors of the pancreas )

CHATAL et al, world J. surg. 24 (2000): 1285-1289 (nuclear medicine applications for neuroendocrine tumors)

            COIT, Ann. Surg. Oncol. 8 (Suppl 9) (2001); 99 – 102 (Merkel cell     

            carcinoma)

De HERDER and LAMBERTS, Curr, Opin. Oncol. 14 (2002); 53-57 (somatostatin and analogs: diagnostic and therapeutic uses)

            GOESSLING et al, J. Clin. Oncol. 20 (2002): 588-598

KOPE et al, J. Cancer Res. Clin. Oncol. 127 (2001): 143-155 (magngement of malignant adrenal tumors)

KULKE and MAYER, N. Engl. J. Med. 340 (1999): 858-868 (carcinoid tumors)

MEDINA-FRANCO et al, Ann. Surg. Oncol. 8 (2001): 204-208 (Merkel cell carcinoma)

MITRY and ROUGIER, Crit. Rev. Oncol. Hematol. 37 (2001): 45-51 (treatment of undifferentiated neuroendocrine tumors)

ÖBERG, Curr.  Opin. Oncol. 14 (2002):38-45 (carcinoid tumors); Digestion 62 (Suppl 1) (2000): 92-97 (interferon in the treatment of neuroendocrine intestinal tumors)

ORLANDI et al, Endocr. Relat. Cancer 8 (2001): 135-147 (treatment of medullary thyroid carcinoma)

ROUGIER and MITRY , Digestion 62 (Suppl) (2000): 73-78  (chemotherapy in the treatment of neuroendocrine malignant tumors)

SCARPIGNATO and PELOSINI, Chemotherapy 47 (Suppl 2) (2001): 1-29 (somatostatin analogs)

SCHUSSHEIM et al, Trends Endocrinol. Metab. 12(2001): 173-178 (multiple endocrine neoplasia type 1)

WALTHER et al, World. J. Urol. 17 (1999): 35-39 (pheochromocytoma)

WEBSTER, Baillieres Best Pract. Res. Clin. Endocrinol. Metab. 13 (1999): 395-408 (Prolactinomas)

36.2             Carcinoid tumor

36.2.1      Monotherapy

     Treatment may be attempted with a somatostatin analog , interferon alpha ,        

      5- fluorouracil, or doxorubicin, e.g.

 

36.2.1.1   Octreotide and octreotide long-acting release (LAR) formulation

Octreotide                  100-200µg                       s.c.                        2-3 times daily

         At least 6 weeks and as long as a response is achieved. Dose escalation to x 2 500 

         and 2 x 1000 µg is possible in case of insufficient response.

 

Octreotide LAR           20mg                        i.m.                every 4 wks until               

                                                                                               progression*

          * Supplemental octreotide is needed for approximately 2 weeks after initiation of  

             octreotide LAR as well as for occasional rescue injections.

 

194                                                                                                                       Neuroendocrine Tumors

            Literature:

                       APARICIO et al, Eur. J. Cancer 37 (2001) : 1014 –1019 (antitumor 

                       activity of octreotide and lanreotide in progressive metastatic 

                       neurendocrine tumors)

          ERIKSSON and ÖBERG, Ann. Oncol. 10 (Suppl2) (1999): 31-38 (review  

          of 15 years of somatostatin analogs)

          RICCI et al, Ann. Oncol. 11 (2000):1127-1130 (octreotide LAR in patients 

          with metastatic neuroendocrine tumors pretreated with lanreotide)

          RUBIN et al, J. Clin. Oncol. 17 (1999): 600-606 (octreotide LAR vs

          s.c.octreotide in maliganat carcinoid syndrome)

 

36.2.1.2                     Lanreotide

Lanreotide               30mg /kg                    i.v.                            every 2 wks

                                                                                                    until progression

 

            Literature:

                    APARICIO et al, Eur. J. Cancer 37 (2001): 1014-1019 (antitumor activity 

                    of  octreotide and lanreotide in progressive metastatic neurendocrine tumors)

                    RICCI et al, Am. J. Clin. Oncol. Cancer Clin. Trials 23 (2000): 412-415

                    WYMENGA et al, J. Clin. Oncol. 17 (1999): 1111-1117

 

36.2.1.3                     Interferon alph

Interferon alpha                 5x106 IU                        s.c.                  d 1, 3, 5 

            To be repeated weekly (at least 6 times; in case of a response until progression)

            Literature:

                        DIRIX et al, Anticancer Drugs 7 (1996); 175- 181

                        ÖBERG, Digestion 57 (Suppl 1) (1996): 81-83

 

36.2.1.4                    Doxorubicin

Doxorubicin                60mg/m2                        i.v. (bolus)                     d 1

            To be repeated every 3-4 weeks

 

            Literature:

ENGSTROM and LAVIN. J. Clin. Oncol. 2 (1984): 1255-1259 (streptozotocin + 5- fluorouracil vs doxorubicin)

36.2.1.5  5- fluorouracil

5-Fluorouracil               500mg /m2                       i.v.(bolus)                     d 1-5

            To be repeated every 5 weeks

            Literature:

                        MOERTEL, J. Clin. Oncol. 1 (1984): 727-740

 

36.2.2.                       Combination chemotherapy

No clear advantage compared to montherapy. e.g.

 

36.2.2.1           5-Fluorouracil + streptozotocin

5-Fluorouracil                 400mg/m2                       i.v.(bolus)                          d 1-5

Streoptozotocin              500 mg/m2                       i.v.( short inf)                    d 1-5

            To be repeated every 6 weeks

 

            Literature:        

                   MOERTEL and HANLEY, Cancer Clin. Trials 2 (1979): 327-334

 

Neurooendocrine Tumors                                                                                                                             195

 

36.2.2.2  Etoposide + cisplatin

Etoposide                      130mg/m2                          i.v.(24 h inf)                     d 1-3

Cisplatin                       45 mg/m2                           i.v.( 24 h inf)                     d 2-3

            To be repeated every 4 weeks (max 6 cycles)

            Literature:

                        MOERTEL et al, Cancer 68  (1991): 227 – 232

 

36.3          Islet cell cancer of the pancreas

Treatment may be attempted with somatostatin analogs, or interferon alpha, or streptozotocin, or doxorubicin, or combinations of streptozotocin with 5-fluorouracil or with doxorubicin, or etoposide + cisplatin (see 35.2).

 

Literature:

            ERIKSSON et al, Cancer 65 (1990): 1883-1890

            KVOLS and BUCK, Semin, Oncol. 14 (1987): 343-353

            MOERTEL, J. Clin. Oncol. 5 (1987): 1503-1522

            ÖBERG, Ann. Oncol. 7 (1996): 453-463

36.4          Medullary carcinoma of the thyroid

 

36.4.1   Monotherapy

Treatment may be attempted with octreotide, or interferon alpha, or doxorubicin (see 36.2).

 

Literature:

            GOTTLIEB and HILL, N. Engl. J. Med. 290 (1974): 193-197

            (doxorubicin)

36.4.2   Combination chemotherapy

E.g.  CVD

Cyclophosphamide                750 mg/m2                i.v. (bolus)                      d 1

Vincristine                            1.4 mg/m2                  i.v.( bolus)                      d 1

Dacarbazine                           600 mg/m2                i.v. (bolus)                      d 1+ 2

            To be repeated every 3-4 weeks (4-6 cycles)

 

            Literature:

                        WU et sl, Cancer 73 (1994): 432-436

36.5.      Adrenal cortical carcinoma

36.5.1 Mitotane (o, p ‘ DDD, Lysodren )

Mitotane                      up to 10 g/d                     p.o.                    in 3 divided doses

                                                                                                       for to months

Pharmacokinetic monitoring of serum concentrations might be of value with target concentrations > 14 µg/ml being associated with a greater chance of reponse. To offset adrenal insufficiency induced by mitotane, hydrocortisone (30 – 60 mg/d) and fludrocortisone (50mg/d) are administered orally, starting after the second week of mitotane treatment.

 

Literature:

            BOVEN et al, Cancer 53 (1984): 26-29

            Van SLOOTEN et al, Eur. J. Cancer Clin. Oncol. 20 (1984): 47-53

            WOOTEN and KING, Cancer 72 (1993): 145-155

 

196                                                                                                                        Neuroendocrine Tumors

 

36.5.2.                       Chemotherapy

May be attempted with cisplatin ± etoposide, doxorubicin;  also in association with mitotane , e.g.

 

36.5.2.1 Cisplatin

Cisplatin                         100mg./m2                       i.v.( 2 h inf)                     d 1

            To be repeated every 3 weeks

            Literature:

                        DHUN et al, Cancer Treat. Rep. 67 (1983): 513-514

 

36.5.2.2  Doxorubicin

Doxorubicin                       60 mg/m2                           i.v.( bolus)                     d 1

            To be repeated every 3 weeks

            Literature:

                        DECKER and KUEHNER. Am. Surg. 57 (1991): 502-513

 

36.5.2.3  EAP – M

Doxorubicin                  20 mg/m2                          i.v.( bolus)                       d 1+8

Cisplatin                       40 mg/m2                           i.v.( 1 h inf)                     d 2+9

Etoposide                      100mg/m2                          i.v.(1 h inf)                     d 5-7

            To be repeated every 4 weeks (max 6 cycles) plus

Mitotane                              maximum tolerated dose ( up to 4 g/d ), continuously

                                             until progression or onset of severe toxicity

 

            Literature:

                        BERRUTI et al, Cancer 83 (1998): 2194 –2200

 

36.5.3         In case of hormone hypersecretion

Palliation (but no inhibition of tumor growth) may be achieved with ketoconazole aminoglutethimide or metyrapone.

 

36.6                Pheochromocytoma

CVD see 36.4.2

 

Literature :

            AVERBUCH et al, Ann. Intern. Med. 109 (1988): 267 – 273

 

36.7                prolactinomas

Treatment with dopamin agonists (cabergoline, quinagolide are better tolerated and more effective than bromocriptine ). Withdrawal or dose reduction should be considered after 2-5 years of therapy .

 

Literature:

WEBSTER, Baillieres Best Pract. Res. Clin. Endocrinol. Metab. 13 (1999): 395 – 408 (review)

Neurooendocrine Tumors                                                                                                                             197

36.8                Merkel cell tumors

Effective cytostatics are etoposide, cyclophosphamide, cisplatin, methotrexate, doxorubicin, 5-fluorouracil and vinca alkaloids. Treatment can be attempted with combination chemotherapy regimens used for small cell lung cancer.

Literature: e.g.

            FENIG et al, Cancer 80 (1997): 881-885

            HENSE  et al, Tumor Diagn . Ther. 19 (1998): 123-137

            PECTASIDES et al, Am. J. Clin. Oncol. (CCT) 18 (1995): 418-420

                       TAI et al, J. Clin. Oncol. 18 (2000): 2493-2499

 

36.9                Generally applicable

(Carcinoid, islet cell cancer of the pancreas, medullary carcinoma of the thyroid)

5-Fluorouracil                  400mg/m2                 i.v.                                      d 1-3

Dacarbazine                     200 mg/m2                i.v. (30 min inf)                  d 1-3

Etoposide                        30mg/m2                    i.v.                                      d 1-3

To be repeated every 3 weeks (max 9 cycles)

            Literature: e.g.

                        BAJETTA et al, Cancer 83 (1998): 372-378

 

36.10            Radiopharmaceuticals

Sensitive, specific radiopharmaceuticals are available for diagnosis ([123]I-

Metaiodobenzylguanidine for pheochromocytoma, [111] In- labeled somatostatin         

analog octreotide for gastroenteropancreatic and carcinoid tumors), and  therapy ([131])I-metaiodobenzylguanidine, [90]Y-octreotide).

 

Literature: e.g.

            CHATAL et al, World J. Surg. 24 (2000): 1285-1289

            De JONG et al, Int. J. Cancer 75 (1998): 406 –411

            LEIMER et al, J Nucl. Med. 39 (1998): 2090-2094

            SMITH- JONES et al, Nucl. Med. Biol. 25 (1998): 181-188